RATIONALE:Circumcision is one of the most frequently used surgical procedures worldwide. Extensive penile skin defects, which can occur as a rare but severe complication of circumcision, are serious and frustrating problems for patients who experience them. Procedures for correcting these problems can pose a challenge to plastic surgeons in the clinic. PATIENT CONCERNS:A 31-year-old man was admitted to our care with an extensive defect of the penile skin caused by a circumcision performed 20 days previously. PRIMARY DIAGNOSES:Infection, necrosis, and defects of the penile skin. INTERVENTIONS:A reverse bilateral anterior scrotal flap was used to correct complete penile skin loss following debridement of the infected and necrotic tissue. OUTCOMES:The patient experienced no complications during the 10-year follow-up period. The patient reported normal erectile function and the ability to perform intercourse. LESSONS:The reverse bilateral anterior scrotal artery flap is suitable for repairing skin defects of the penis and allows for satisfactory cosmetic and functional improvement following defects of the penile skin.